Megacolon Caused by Hirschsprung's Disease in Pregnant Women from a Rural Area in Indonesia: A Case Report

Authors

  • Hadisubroto Yonas Department of Obstetrics and Gynecology, Dr. Soebandi Regional Hospital, Jember, East Java, Indonesia
  • Nugroho Adi Department of Surgery, Dr. Soebandi Regional Hospital, Jember, East Java, Indonesia.
  • Supangat Supangat Department of Surgery, Dr. Soebandi Regional Hospital, Jember, East Java, Indonesia & Faculty of Medicine, University of Jember, Jember, East Java, Indonesia.
  • Zahradiasti Chansa Zuhdi Faculty of Medicine, University of Jember, Jember, East Java, Indonesia.
  • Fitriyah Ainun Nadiratul Faculty of Medicine, University of Jember, Jember, East Java, Indonesia.
  • Nuridah Ayu Liliana Faculty of Medicine, University of Jember, Jember, East Java, Indonesia.
  • Ika Rahmawati Sutejo Department of Biochemistry, Faculty of Medicine, University of Jember, Jember, East Java, Indonesia.

Keywords:

Congenital, Hirschsprung, Pregnancy, Rural community

Abstract

This case report describes a rare occurrence of Hirschsprung's disease presenting in a 26-year-old pregnant woman from a rural area in Indonesia. Initially asymptomatic for pregnancy-related issues, the patient had experienced lifelong constipation, frequently managed with laxatives, and had significant abdominal distension. At approximately 34-35 weeks of gestation, an ultrasound during a routine obstetric check-up revealed intestinal dilation potentially compressing the uterus. Subsequent referral to a regional hospital confirmed the diagnosis of Hirschsprung's disease, differentiated from teratoma through imaging and postoperative findings. A classical caesarean section was performed at 38 weeks, during which a significantly dilated sigmoid megacolon and fecaloma were discovered and managed with a distal colostomy. This case highlights the challenges of diagnosing and managing rare gastrointestinal disorders in pregnant patients, emphasizing the importance of
considering congenital anomalies in differential diagnoses to ensure appropriate prenatal care and surgical intervention.

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Published

2024-06-03

How to Cite

Yonas, H., Adi, N., Supangat, S., Zuhdi, Z. C., Nadiratul, F. A., Liliana, N. A., & Sutejo, I. R. (2024). Megacolon Caused by Hirschsprung’s Disease in Pregnant Women from a Rural Area in Indonesia: A Case Report. Journal of the Dow University of Health Sciences (JDUHS), 18(3), 181–184. Retrieved from https://jduhs.jduhs.duhs.edu.pk/index.php/jduhs/article/view/1926

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Section

Case Report